TextbookHaematologyWaldenstrom Macroglobulinaemia

Waldenstrom Macroglobulinaemia

B-cell lymphoproliferative disorder characterised by bone marrow infiltration with lymphoplasmacytic lymphoma and production of monoclonal IgM paraprotein.

Key Facts

Waldenström macroglobulinaemia (WM) is a rare lymphoplasmacytic lymphoma producing monoclonal IgM paraprotein Incidence approximately 3 per million per year in the UK; median age at diagnosis 65-70 years MYD88 L265P mutation found in >90% of cases – key diagnostic marker distinguishing from other IgM-producing lymphomas Hyperviscosity syndrome occurs in 10-30% due to pentameric IgM structure causing increased serum viscosity First-line treatment: rituximab-based chemotherapy (e.g., DRC: dexamethasone, rituximab, cyclophosphamide) Ibrutinib 420mg OD (BTK inhibitor) is effective in relapsed/refractory disease and increasingly used first-line Median overall survival is approximately 5-8 years with treatment

Overview

Key Facts

Waldenström macroglobulinaemia is a lymphoplasmacytic lymphoma characterised by infiltration of the bone marrow by clonal lymphoplasmacytic cells and secretion of monoclonal IgM. The large pentameric IgM molecule predisposes to hyperviscosity syndrome.

Epidemiology

  • Rare: approximately 1,500 people living with WM in the UK
  • Median age at diagnosis: 65-70 years
  • Male predominance (M:F ratio 2:1)
  • More common in White European populations
  • Accounts for 1-2% of haematological malignancies

Aetiology

  • Exact cause unknown; often preceded by IgM MGUS
  • IgM MGUS progresses to WM at 1.5% per year
  • MYD88 L265P mutation is present in >90% (activates NF-κB signalling)
  • CXCR4 mutations in ~30% (associated with resistance to ibrutinib)
  • Familial clustering observed; first-degree relatives have 20-fold increased risk

Pathophysiology

  • Clonal B-cell lymphoplasmacytic proliferation in bone marrow
  • Overproduction of monoclonal IgM (pentameric) → markedly raised serum viscosity
  • Hyperviscosity: IgM is the largest immunoglobulin → sludging of blood in microcirculation
  • Bone marrow infiltration → cytopenias (anaemia most common)
  • IgM may act as autoantibody → cold agglutinin disease, peripheral neuropathy, cryoglobulinaemia
  • Unlike myeloma, lytic bone lesions are rare

Clinical Presentation

Constitutional Symptoms

  • Fatigue (most common, due to anaemia)
  • Weight loss, night sweats
  • Hepatosplenomegaly and lymphadenopathy (more common than in myeloma)

Hyperviscosity Syndrome (10-30%)

  • Visual disturbance: blurred vision, diplopia
  • Headache, confusion, somnolence
  • Mucosal bleeding: epistaxis, gingival bleeding
  • Fundoscopy: engorged retinal veins ("sausage-link" appearance), papilloedema, retinal haemorrhages

IgM-Related Complications

  • Peripheral neuropathy (20-25%): anti-MAG antibodies → sensorimotor neuropathy
  • Cold agglutinin disease: Raynaud phenomenon, acrocyanosis, haemolytic anaemia in cold
  • Cryoglobulinaemia: purpura, arthralgia, renal involvement
  • AL amyloidosis (rare)

Red Flags

  • Sudden visual loss or severe headache → hyperviscosity emergency → urgent plasmapheresis
  • Rapidly worsening cytopenias → marrow failure
  • Unexplained neuropathy with IgM paraprotein → investigate for WM

Differential Diagnosis

DiagnosisKey FeaturesInvestigation
IgM MGUSIgM <30 g/L, no symptoms, no marrow infiltrationSPEP, bone marrow
Multiple myelomaIgG/IgA paraprotein (rarely IgM), lytic lesions, CRABSPEP, imaging, marrow
Marginal zone lymphomaMay produce IgM, splenic involvementCT, bone marrow, flow cytometry
CLLLymphocytosis, smear cells, rarely IgM paraproteinBlood film, flow cytometry
Primary amyloidosisOrgan deposition, various Ig typesCongo red stain, SAP scan
Cryoglobulinaemia (Hep C)HCV-associated, vasculitis, mixed cryoglobulinsCryoglobulins, HCV serology

Diagnosis / Investigation

Bedside

  • Fundoscopy: hyperviscosity changes (dilated veins, haemorrhages)
  • Peripheral neurological examination: neuropathy assessment

Bloods

  • FBC: anaemia (normocytic), may show rouleaux
  • SPEP and immunofixation: monoclonal IgM band
  • Serum IgM level: typically >30 g/L
  • Serum free light chains
  • Serum viscosity: >4 cP associated with hyperviscosity symptoms
  • Beta-2 microglobulin: prognostic
  • LDH: prognostic
  • DAT (Coombs test): if cold agglutinin disease suspected
  • Cryoglobulins: if cryoglobulinaemia suspected
  • Hepatitis B and C serology: exclude HCV-associated cryoglobulinaemia

Imaging

  • CT neck/chest/abdomen/pelvis: lymphadenopathy, hepatosplenomegaly
  • MRI brain: if CNS involvement suspected (Bing-Neel syndrome)

Special Tests

  • Bone marrow aspirate and trephine: lymphoplasmacytic infiltrate, confirm clonality
  • MYD88 L265P mutation testing: present in >90% (helps distinguish from marginal zone lymphoma)
  • CXCR4 mutation testing: treatment implications
  • Nerve conduction studies: if neuropathy present
  • Anti-MAG antibodies: if peripheral neuropathy

Management

Non-pharmacological

  • Watch and wait if asymptomatic (smouldering WM) – regular monitoring
  • Treatment indicated for: symptomatic hyperviscosity, cytopenias, neuropathy, constitutional symptoms, amyloidosis, cryoglobulinaemia

Pharmacological

First-line:

  • DRC regimen: dexamethasone 20mg IV day 1 + rituximab 375 mg/m² IV + cyclophosphamide 100 mg/m² BD PO days 1-5, q21 days × 6 cycles
  • Alternative: bendamustine-rituximab (BR): bendamustine 90 mg/m² IV days 1-2 + rituximab, q28 days × 6
  • Ibrutinib 420mg OD – increasingly used first-line, particularly if MYD88 mutated
  • Avoid rituximab monotherapy initially if IgM >40 g/L (risk of IgM flare)

Hyperviscosity emergency:

  • Urgent plasmapheresis to rapidly reduce IgM levels
  • Followed by systemic chemotherapy

Relapsed disease:

  • Ibrutinib, zanubrutinib, venetoclax, bortezomib-based regimens
  • Zanubrutinib 160mg BD (ASPEN trial) – second-generation BTK inhibitor

Referral Criteria

  • All patients with IgM paraprotein → haematology
  • Acute visual loss or neurological symptoms → urgent assessment for plasmapheresis

Prognosis

  • Median overall survival: 5-8 years with modern therapy
  • International Prognostic Scoring System for WM (IPSSWM): age >65, Hb ≤115 g/L, platelets ≤100, β2M >3, IgM >70 g/L
  • Low-risk IPSSWM: 5-year survival 87%
  • High-risk IPSSWM: 5-year survival 36%
  • Risk of transformation to DLBCL (diffuse large B-cell lymphoma) in 5-10%
  • Neuropathy can be debilitating and may not fully resolve with treatment

Other Relevant Information

IPSSWM Prognostic Scoring

Risk FactorCriterion
Age>65 years
Haemoglobin≤115 g/L
Platelets≤100 × 10⁹/L
β2-microglobulin>3 mg/L
IgM level>70 g/L
Risk GroupFactors5-year Survival
Low0-1 (except age)87%
Intermediate2 or age only68%
High≥336%

Key Differences: WM vs Multiple Myeloma

FeatureWMMyeloma
ParaproteinIgMIgG/IgA (rarely IgM)
Bone lesionsRareCommon (lytic)
HyperviscosityCommon (10-30%)Rare
LymphadenopathyCommonRare
MYD88 mutation>90%Rare