TextbookRenal MedicineHaemolytic Uraemic Syndrome

Haemolytic Uraemic Syndrome

Thrombotic microangiopathy characterised by the triad of microangiopathic haemolytic anaemia (MAHA), thrombocytopenia, and acute kidney injury. Typical (Shiga toxin-associated) HUS is most common in children following E. coli O157:H7 gastroenteritis. Atypical HUS is complement-mediated and requires eculizumab.

Key Facts

HUS is defined by the triad of MAHA (fragmented RBCs), thrombocytopenia, and AKI Typical HUS (90% of childhood cases): caused by Shiga toxin-producing E. coli (STEC), most commonly O157:H7; follows bloody diarrhoea Atypical HUS (aHUS): complement-mediated (Factor H, Factor I, MCP mutations, anti-Factor H antibodies); not preceded by diarrhoea Blood film: schistocytes (fragmented red blood cells) are characteristic of MAHA Typical HUS: supportive management only – IV fluids, dialysis if needed; do NOT give antibiotics (may increase toxin release) Atypical HUS: eculizumab (anti-C5 monoclonal antibody) is first-line – dramatically improves outcomes (NICE TA694) Typical HUS prognosis: 90-95% recover renal function; mortality <5% in children Do NOT transfuse platelets unless active life-threatening bleeding (worsens thrombotic process)

Overview

Key Facts

HUS is a medical emergency requiring urgent recognition. The distinction between typical (STEC) and atypical (complement-mediated) HUS is critical as management differs fundamentally.

Epidemiology

  • Typical HUS: peak age 6 months to 5 years; incidence ~1.5 per 100,000 children/year in the UK
  • aHUS: much rarer; ~0.5 per million/year; any age
  • Leading cause of AKI in children

Aetiology

Typical HUS:

  • STEC (Shiga toxin-producing E. coli) O157:H7 (most common), O104:H4
  • Source: undercooked beef, unpasteurised milk, contaminated water/produce
  • 5-15% of STEC infections develop HUS

Atypical HUS:

  • Complement dysregulation: mutations in Factor H (25%), Factor I, MCP (CD46), C3, Factor B
  • Anti-Factor H antibodies (especially children)
  • Acquired: pregnancy, drugs (ciclosporin, tacrolimus, quinine), transplant

Pathophysiology

  • Typical: Shiga toxin binds Gb3 receptors on renal endothelium → endothelial damage → platelet activation → microthrombi in glomerular capillaries → MAHA + thrombocytopenia + AKI
  • Atypical: uncontrolled alternative complement pathway activation → C5b-9 (MAC) formation on endothelial surfaces → thrombotic microangiopathy
  • Red blood cells fragment as they pass through occluded microcirculation → schistocytes

Clinical Presentation

Typical HUS

  • Prodromal illness: bloody diarrhoea (3-10 days before HUS onset)
  • Pallor and jaundice (MAHA)
  • Oliguria/anuria (AKI)
  • Petechiae/purpura (thrombocytopenia)
  • Oedema and hypertension
  • Lethargy, irritability

Atypical HUS

  • No preceding diarrhoeal illness
  • May present at any age
  • Similar triad: MAHA, thrombocytopenia, AKI
  • Can be triggered by pregnancy, infection, drugs
  • Relapsing-remitting course

Red Flags

  • Anuria → urgent dialysis
  • Seizures, altered consciousness → cerebral involvement (10%)
  • Severe hypertension → encephalopathy risk
  • No diarrhoeal prodrome → think aHUS → urgent complement studies and eculizumab

Differential Diagnosis

DiagnosisKey FeaturesInvestigation
TTPADAMTS13 <10%, neurological predominanceADAMTS13 activity
DICProlonged PT/APTT, low fibrinogen, multi-organCoagulation screen
Pre-eclampsia/HELLPPregnancy, hypertension, liver dysfunctionPregnancy test, LFTs
Malignant hypertensionVery high BP, papilloedema, MAHABP, fundoscopy
SLE with TMAANA positive, multi-systemImmunology

Diagnosis / Investigation

Bloods

  • FBC: anaemia (Hb often <80 g/L), thrombocytopenia (often <50 × 10⁹/L)
  • Blood film: schistocytes (fragmented RBCs) – diagnostic of MAHA
  • Reticulocyte count: raised (haemolysis)
  • LDH: markedly elevated (haemolysis and tissue damage)
  • Haptoglobin: low/absent (consumed in haemolysis)
  • Direct Coombs test: NEGATIVE (distinguishes from AIHA)
  • U&Es: raised creatinine, often severe AKI
  • Coagulation: PT and APTT usually NORMAL (distinguishes from DIC)
  • ADAMTS13 activity: >10% (excludes TTP; <10% = TTP)

Microbiology

  • Stool culture: for STEC (E. coli O157); PCR for Shiga toxin genes
  • Serology: for STEC if stool negative

Special Tests

  • Complement studies (if aHUS suspected): C3, C4, Factor H, Factor I, MCP
  • Anti-Factor H antibodies: especially in children
  • Genetic testing: complement gene mutations
  • Renal biopsy: shows TMA; not routinely needed for diagnosis

Management

Typical (STEC-HUS)

  • Supportive care: IV fluids, monitor fluid balance, electrolytes, BP
  • Dialysis: if severe AKI (indications as per standard)
  • Red cell transfusion: if Hb <60-70 g/L
  • DO NOT give antibiotics: may increase Shiga toxin release and worsen HUS
  • DO NOT transfuse platelets: unless life-threatening bleeding (worsens microthrombosis)
  • Antihypertensives: as needed
  • Monitoring: daily FBC, U&Es, LDH, reticulocytes
  • Notification: STEC is notifiable to public health

Atypical HUS

  • Eculizumab (anti-C5 monoclonal antibody): first-line (NICE TA694)
    • Induction: 900mg IV weekly × 4 weeks, then 1200mg every 2 weeks
    • Dramatic improvement in outcomes
    • Must vaccinate against meningococcus (serogroups ACWY and B) before starting; prophylactic antibiotics if urgent
  • Plasma exchange: bridge while awaiting eculizumab; effective for anti-Factor H antibody-mediated aHUS
  • Immunosuppression: for anti-Factor H antibodies (rituximab, mycophenolate)

Referral

  • All HUS → paediatric/adult nephrology
  • aHUS → tertiary centre with complement expertise
  • Public health notification for STEC

Prognosis

  • Typical HUS in children: mortality <5%; 90-95% recover renal function; 5-10% develop CKD
  • Typical HUS in adults: higher mortality (10-25%) and greater CKD risk
  • Atypical HUS without eculizumab: >50% progress to ESRD or die within first episode
  • Atypical HUS with eculizumab: >80% achieve haematological remission; significant renal recovery
  • Transplant: aHUS recurs in 50-80% of transplants without eculizumab prophylaxis

Other Relevant Information

HUS vs TTP

FeatureHUSTTP
AgeChildren (typical)Adults
ADAMTS13>10%<10%
Renal involvementPredominantVariable
NeurologicalLess commonPredominant
Diarrhoeal prodromeYes (typical)No
TreatmentSupportive (typical) / Eculizumab (atypical)Plasma exchange + caplacizumab

Complement Mutations in aHUS

GeneFrequencyRecurrence Risk
Factor H25%High (75%)
MCP (CD46)10%Low (20%)
Factor I5-10%High (70%)
C35-10%High (50%)
Factor B1-2%High